Entry - 608808 - TRANSPOSITION OF THE GREAT ARTERIES, DEXTRO-LOOPED; DTGA - OMIM - (MIRROR)
608808

TRANSPOSITION OF THE GREAT ARTERIES, DEXTRO-LOOPED; DTGA


Alternative titles; symbols

DTGA1


Clinical Synopsis
 

INHERITANCE
- Autosomal dominant
CARDIOVASCULAR
Vascular
- Dextro-looped transposition of the great arteries
MISCELLANEOUS
- Incomplete penetrance

TEXT

Description

The more common form of transposition of the great arteries, dextro-looped TGA, consists of complete inversion of the great vessels, so that the aorta incorrectly arises from the right ventricle and the pulmonary artery incorrectly arises from the left ventricle. (In the less common type of TGA, levo-looped TGA, the ventricles are inverted instead) (Goldmuntz et al., 2002). This creates completely separate pulmonary and systemic circulatory systems, an arrangement that is incompatible with life. Patients with TGA often have atrial and/or ventricular septal defects or other types of shunting that allow some mixing between the circulations in order to support life minimally, but surgical intervention is always required.


Nomenclature

The symbol 'DTGA2' was originally used to designate isolated cardiac malformations associated with mutations in the CFC1 gene (605194) on chromosome 2; DGTA2 has since been reclassified as a variant of a heterotaxy syndrome (HTX2; 605376). The symbol 'DTGA3' was formerly used for transposition of the great arteries caused by mutation in the GDF1 gene (602880); the symbol for the multiple types of congenital heart defects caused by mutation in GDF1, including TGA, is CHTD6 (613854).


Inheritance

Becker et al. (1996) reported the frequency of cardiovascular malformations in first-degree relatives of probands with transposition of the great arteries. Patients were subdivided into levo-TGA (19), dextro-TGA (168), complex TGA (65), and asplenia with TGA (19). In the levo-TGA group, 1 of 50 sibs had a cardiovascular malformation while all parents were normal. In the dextro-TGA group, 1 of 369 sibs had cardiovascular malformation, and 1 father had levo-TGA. Four of 143 sibs in the complex-TGA group and 2 of the parents had cardiovascular malformation, and in the asplenia with TGA group, 1 of 50 sibs and no parents had a heart defect. Overall recurrence risk in sibs was 5 in 612 (0.82%).


Molecular Genetics

Associations Pending Confirmation

In a screening of 97 patients with isolated DTGA for mutations in the PROSIT240 gene (MED13L; 608771), Muncke et al. (2003) identified 6 intronic polymorphisms, 6 silent mutations, and 4 missense mutations. Three of the heterozygous missense mutations (E251G, 608771.0001; R1872H, 608771.0002; and D2023G, 608771.0003) appeared to be disease causing, although there was evidence for incomplete penetrance in 1 family. Functional studies of the variants were not performed. The patient they reported with the E251G mutation had additional features and was later diagnosed with MRFACD (616789).


REFERENCES

  1. Becker, T. A., Van Amber, R., Moller, J. H., Pierpont, M. E. M. Occurrence of cardiac malformations in relatives of children with transposition of the great arteries. Am. J. Med. Genet. 66: 28-32, 1996. [PubMed: 8957507, related citations] [Full Text]

  2. Goldmuntz, E., Bamford, R., Karkera, J. D., dela Cruz, J., Roessler, E., Muenke, M. CFC1 mutations in patients with transposition of the great arteries and double-outlet right ventricle. Am. J. Hum. Genet. 70: 776-780, 2002. [PubMed: 11799476, images, related citations] [Full Text]

  3. Muncke, N., Jung, C., Rudiger, H., Ulmer, H., Roeth, R., Hubert, A., Goldmuntz, E., Driscoll, D., Goodship, J., Schon, K., Rappold, G. Missense mutations and gene interruption in PROSIT240, a novel TRAP240-like gene, in patients with congenital heart defect (transposition of the great arteries). Circulation 108: 2843-2850, 2003. [PubMed: 14638541, related citations] [Full Text]


Ada Hamosh - updated : 9/22/2021
Cassandra L. Kniffin - updated : 2/4/2016
Marla J. F. O'Neill - updated : 11/20/2015
Cassandra L. Kniffin - updated : 11/12/2015
Marla J. F. O'Neill - updated : 1/26/2015
Victor A. McKusick - updated : 10/10/2007
Creation Date:
Marla J. F. O'Neill : 7/20/2004
carol : 12/13/2021
carol : 09/22/2021
carol : 04/18/2018
carol : 11/21/2017
carol : 02/05/2016
ckniffin : 2/4/2016
carol : 11/20/2015
ckniffin : 11/12/2015
carol : 1/27/2015
carol : 1/27/2015
mcolton : 1/26/2015
joanna : 1/13/2015
carol : 3/31/2011
alopez : 10/15/2007
alopez : 10/15/2007
terry : 10/10/2007
carol : 7/20/2004

608808

TRANSPOSITION OF THE GREAT ARTERIES, DEXTRO-LOOPED; DTGA


Alternative titles; symbols

DTGA1


ORPHA: 860;   DO: 0060770;  



TEXT

Description

The more common form of transposition of the great arteries, dextro-looped TGA, consists of complete inversion of the great vessels, so that the aorta incorrectly arises from the right ventricle and the pulmonary artery incorrectly arises from the left ventricle. (In the less common type of TGA, levo-looped TGA, the ventricles are inverted instead) (Goldmuntz et al., 2002). This creates completely separate pulmonary and systemic circulatory systems, an arrangement that is incompatible with life. Patients with TGA often have atrial and/or ventricular septal defects or other types of shunting that allow some mixing between the circulations in order to support life minimally, but surgical intervention is always required.


Nomenclature

The symbol 'DTGA2' was originally used to designate isolated cardiac malformations associated with mutations in the CFC1 gene (605194) on chromosome 2; DGTA2 has since been reclassified as a variant of a heterotaxy syndrome (HTX2; 605376). The symbol 'DTGA3' was formerly used for transposition of the great arteries caused by mutation in the GDF1 gene (602880); the symbol for the multiple types of congenital heart defects caused by mutation in GDF1, including TGA, is CHTD6 (613854).


Inheritance

Becker et al. (1996) reported the frequency of cardiovascular malformations in first-degree relatives of probands with transposition of the great arteries. Patients were subdivided into levo-TGA (19), dextro-TGA (168), complex TGA (65), and asplenia with TGA (19). In the levo-TGA group, 1 of 50 sibs had a cardiovascular malformation while all parents were normal. In the dextro-TGA group, 1 of 369 sibs had cardiovascular malformation, and 1 father had levo-TGA. Four of 143 sibs in the complex-TGA group and 2 of the parents had cardiovascular malformation, and in the asplenia with TGA group, 1 of 50 sibs and no parents had a heart defect. Overall recurrence risk in sibs was 5 in 612 (0.82%).


Molecular Genetics

Associations Pending Confirmation

In a screening of 97 patients with isolated DTGA for mutations in the PROSIT240 gene (MED13L; 608771), Muncke et al. (2003) identified 6 intronic polymorphisms, 6 silent mutations, and 4 missense mutations. Three of the heterozygous missense mutations (E251G, 608771.0001; R1872H, 608771.0002; and D2023G, 608771.0003) appeared to be disease causing, although there was evidence for incomplete penetrance in 1 family. Functional studies of the variants were not performed. The patient they reported with the E251G mutation had additional features and was later diagnosed with MRFACD (616789).


REFERENCES

  1. Becker, T. A., Van Amber, R., Moller, J. H., Pierpont, M. E. M. Occurrence of cardiac malformations in relatives of children with transposition of the great arteries. Am. J. Med. Genet. 66: 28-32, 1996. [PubMed: 8957507] [Full Text: https://doi.org/10.1002/(SICI)1096-8628(19961202)66:1<28::AID-AJMG7>3.0.CO;2-S]

  2. Goldmuntz, E., Bamford, R., Karkera, J. D., dela Cruz, J., Roessler, E., Muenke, M. CFC1 mutations in patients with transposition of the great arteries and double-outlet right ventricle. Am. J. Hum. Genet. 70: 776-780, 2002. [PubMed: 11799476] [Full Text: https://doi.org/10.1086/339079]

  3. Muncke, N., Jung, C., Rudiger, H., Ulmer, H., Roeth, R., Hubert, A., Goldmuntz, E., Driscoll, D., Goodship, J., Schon, K., Rappold, G. Missense mutations and gene interruption in PROSIT240, a novel TRAP240-like gene, in patients with congenital heart defect (transposition of the great arteries). Circulation 108: 2843-2850, 2003. [PubMed: 14638541] [Full Text: https://doi.org/10.1161/01.CIR.0000103684.77636.CD]


Contributors:
Ada Hamosh - updated : 9/22/2021
Cassandra L. Kniffin - updated : 2/4/2016
Marla J. F. O'Neill - updated : 11/20/2015
Cassandra L. Kniffin - updated : 11/12/2015
Marla J. F. O'Neill - updated : 1/26/2015
Victor A. McKusick - updated : 10/10/2007

Creation Date:
Marla J. F. O'Neill : 7/20/2004

Edit History:
carol : 12/13/2021
carol : 09/22/2021
carol : 04/18/2018
carol : 11/21/2017
carol : 02/05/2016
ckniffin : 2/4/2016
carol : 11/20/2015
ckniffin : 11/12/2015
carol : 1/27/2015
carol : 1/27/2015
mcolton : 1/26/2015
joanna : 1/13/2015
carol : 3/31/2011
alopez : 10/15/2007
alopez : 10/15/2007
terry : 10/10/2007
carol : 7/20/2004